H3B-8800, an orally available small-molecule splicing modulator, induces lethality in spliceosome-mutant cancers.

نویسندگان

  • Michael Seiler
  • Akihide Yoshimi
  • Rachel Darman
  • Betty Chan
  • Gregg Keaney
  • Michael Thomas
  • Anant A Agrawal
  • Benjamin Caleb
  • Alfredo Csibi
  • Eckley Sean
  • Peter Fekkes
  • Craig Karr
  • Virginia Klimek
  • George Lai
  • Linda Lee
  • Pavan Kumar
  • Stanley Chun-Wei Lee
  • Xiang Liu
  • Crystal Mackenzie
  • Carol Meeske
  • Yoshiharu Mizui
  • Eric Padron
  • Eunice Park
  • Ermira Pazolli
  • Shouyong Peng
  • Sudeep Prajapati
  • Justin Taylor
  • Teng Teng
  • John Wang
  • Markus Warmuth
  • Huilan Yao
  • Lihua Yu
  • Ping Zhu
  • Omar Abdel-Wahab
  • Peter G Smith
  • Silvia Buonamici
چکیده

Genomic analyses of cancer have identified recurrent point mutations in the RNA splicing factor-encoding genes SF3B1, U2AF1, and SRSF2 that confer an alteration of function. Cancer cells bearing these mutations are preferentially dependent on wild-type (WT) spliceosome function, but clinically relevant means to therapeutically target the spliceosome do not currently exist. Here we describe an orally available modulator of the SF3b complex, H3B-8800, which potently and preferentially kills spliceosome-mutant epithelial and hematologic tumor cells. These killing effects of H3B-8800 are due to its direct interaction with the SF3b complex, as evidenced by loss of H3B-8800 activity in drug-resistant cells bearing mutations in genes encoding SF3b components. Although H3B-8800 modulates WT and mutant spliceosome activity, the preferential killing of spliceosome-mutant cells is due to retention of short, GC-rich introns, which are enriched for genes encoding spliceosome components. These data demonstrate the therapeutic potential of splicing modulation in spliceosome-mutant cancers.

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عنوان ژورنال:
  • Nature medicine

دوره   شماره 

صفحات  -

تاریخ انتشار 2018